Definition And Classification
- Rare thrombotic microangiopathy (TMA).
- Characterized by systemic microvascular thrombosis leading to end-organ ischemia.
- Categorized into acquired (more common) and congenital forms.
Pathophysiology
- Driven by deficiency of ADAMTS13 (a disintegrin and metalloprotease with thrombospondin type 1 repeats).
- ADAMTS13 normally cleaves unusually large multimers of von Willebrand factor (vWF) into biologically less active forms.
- Deficiency leads to accumulation of ultralarge vWF multimers.
- Results in "spontaneous" platelet adhesion, aggregation, and extensive microvascular thrombosis.
| Type | Pathogenesis | Associated Factors |
|---|---|---|
| Acquired TTP | Autoantibody-mediated inhibition/clearance of ADAMTS13. | Female sex, African-American descent, autoimmune disease, pregnancy, infection, drugs (ticlopidine, clopidogrel). |
| Congenital TTP | Genetic mutation in ADAMTS13 gene (chromosome 9q34); inadequate enzyme production. Abnormal complement system implicated rarely. | Also known as Upshaw-Shulman syndrome. Presents in infancy with jaundice/thrombocytopenia, or triggered later by pregnancy/infection. |
Clinical Features
- Classic pentad of findings (often presenting acutely):
- Microangiopathic hemolytic anemia (MAHA).
- Thrombocytopenia.
- Neurologic symptoms: Subtle, shifting signs, changes in affect/orientation, aphasia, blindness, seizures.
- Renal impairment: Progressive renal failure in 25% of chronic cases.
- Fever.
- Additional symptoms: Pallor, jaundice, malaise, nausea, vomiting, abdominal pain, chest pain.
Diagnostic Evaluation
Laboratory Findings
- Hematology:
- Thrombocytopenia (often severe, out of proportion to hemorrhage).
- MAHA: Polychromasia, basophilic stippling, schistocytes, microspherocytes, helmet cells, burr cells, and nucleated red blood cells on peripheral smear.
- Elevated reticulocyte count.
- Hemolysis Markers:
- Markedly elevated lactate dehydrogenase (LDH).
- Reduced or absent haptoglobin.
- Increased unconjugated bilirubin.
- Hemoglobinuria and hemosiderinuria.
- Immunology: Direct antiglobulin test (DAT/Coombs) negative.
- Coagulation Profile: Usually nondiagnostic; occasionally concurrent disseminated intravascular coagulation (DIC) features (prolonged PT/PTT, elevated D-dimer, hypofibrinogenemia) observed.
- Renal Function: Elevated blood urea nitrogen (BUN) and creatinine.
Confirmatory Testing
- ADAMTS13 Assay: Severe deficiency (activity <10%) confirms diagnosis.
- Autoantibodies: Presence of inhibitory anti-ADAMTS13 IgG autoantibodies confirms acquired TTP.
Clinical Scoring
- PLASMIC Score: Utilized to identify patients with high likelihood of ADAMTS13 deficiency pending assay results.
- Incorporates platelet count, hemolytic anemia, macrocytosis, coagulopathy, renal failure, and history of organ transplantation/malignancy.
Management And Treatment
- Medical emergency; 80-90% mortality without timely intervention.
- Diagnosis made clinically; treatment must initiate immediately without awaiting ADAMTS13 assay results.
Acquired Thrombotic Thrombocytopenic Purpura
| Therapy Modality | Details & Rationale |
|---|---|
| Plasma Exchange (Plasmapheresis) | Mainstay of therapy. Removes anti-ADAMTS13 antibodies and replaces deficient enzyme via donor plasma. Achieves 50-80% remission rate. |
| Corticosteroids | Administered in high doses alongside plasma exchange. |
| Rituximab | Targets B-cells producing ADAMTS13 autoantibodies. Given upfront or in refractory cases to reduce required plasmapheresis sessions and prevent relapse. |
| Caplacizumab | Anti-vWF humanized monoclonal antibody. Blocks platelet interaction with ultralarge vWF multimers. Decreases time to platelet normalization. |
| Platelet Transfusion | Generally contraindicated. Potential to worsen consumptive coagulopathy and microvascular thrombosis. Reserved exclusively for life-threatening emergent bleeding. |
| Refractory/Relapsing Disease | Immunosuppressives (cyclosporine, cyclophosphamide, vincristine, mycophenolate mofetil, azathioprine). Splenectomy considered for refractory cases. |
Congenital Thrombotic Thrombocytopenic Purpura
- Plasma Infusions: Mainstay of therapy. Replaces missing ADAMTS13 enzyme. Autoantibodies absent, obviating need for plasmapheresis.
- Prophylaxis: Scheduled plasma infusions at 2-3 week intervals.
- Novel Therapies: Recombinant ADAMTS13 concentrates (undergoing clinical trials). Plasma-derived Factor VIII concentrates containing ADAMTS13 offer alternative for patients with severe plasma reactions.